Ischemic Neurologic Event in a Child as a Result ofVentricular Septal Aneurysm M. Kowalski, MD, E Hoffman, MD, J. R62afiski, M D , and W. Rydlewska-Sadowska, M D , FESC, Warsaw, Poland Aneurysm of the interventricula~ septum without a shunt was found by means of transthoracic echoeardiography in a 6-year-old boy with acute hemiparesis. Until the time of the incident, he had been healthy. The aneurysmal sac contained 2 clots, p r e s u m a b l y r e s u l t i n g i n t h e i s c h e m i c c e r e b r a l infarct. On the basis of the echocardiographic scan, successful surgery was p e r f o r m e d . To the b e s t o f o u r k n o w l e d g e , t h i s is t h e f i r s t r e p o r t describing such dramatic sequelae of interventric u l a r s e p t a l a n e u r y s m . (J Am Soc Echocardiogr 1998; 11:116i-2.) A n e u r y s m s o f t h e v e n t f i c u l a r s e p t u m are m o s t likely c o n g e n i t a l in origin. 1 T h e y m a y b e a n isolated finding o r may o c c u r w i t h o t h e r cardiac malformations. M e m b r a n o u s a n e u r y s m s t e n d to d e v e l o p as t h e result of incomplete closure of ventricular septal defects. 2 Little is k n o w n a b o u t t h e natural history o f a n e u r y s m s . T h e c o n d i t i o n m a y b e e i t h e r clinically silent o r associated w i t h a left-to-right shunt, ventricular arrhythmia, endocarditis, ventricnlar outflow t r a c t obstruction, o r aortic insufficiency. 1-3 Its unusual e m b o l i c p o t e n t i a l has b e e n r e p o r t e d . 1,4 We d e s c r i b e a p e d i a t r i c c a s e in w h i c h t h r o m b u s f o r m e d inside t h e a n e u r y s m a l sac, resulting in a neurologic ischemic event.To the best of our knowledge, this c o m p l i c a t i o n has n o t b e e n r e p o r t e d previously. tricuspid valve was suspected. On the basis of this finding, infective endocarditis or myxoma was considered, and the boy was referred to the National Institute of Cardiology. On admission, his condition was inlproved.The electrocardiogram showed a regular sinus rh3qhm with a ventricular rate of 80 bpm and right bundie branch block.The chest radiograph was normal. Repeated tmnsthoracic echocardiography disclosed a saccular aneurysm of the ventricular sepmm withom a shunt (Figures 1 and 2).The aneurysmal sac contained 2 clots. No other malformation was detected. The clots were suspected as causing the neurologic event.The boy qualified for surgery and underwent excision of the septal aneurysm and closure of the resultant ventricular septal defect.Two excised masses were round shaped and had diameters of approximately 2 cm and 1 cm. Histologically, the wall of the sac was fibrous.The sac contained tiarombus in the organization stage, without signs of inflammation. Postoperative recovery was uneventf~.At 9 months of follow-up, the boy remains well. CASE R E P O R T A 6-year-old boy was admitted to a city hospital because of an acute complete leā€¢sided hemiparesis. Until that tirne~ he had been healthy. On admission, he was unconscious with spastic left hemiparesis. On the electrocardiogram, there was a regular sinus rhythm with a ventricular rate of 100 bpm.The immediate computed tomographic scan was noncontributory, but the second scan performed 2 weeks later revealed a low-density area consistent with ischemic cerebral infarct. An abnormality of the septal leaflet of the From the Nonmvasive Cardiology Department, National Institute of Cardiology, Warsaw, Poland. Reprint requests: Miroslaw Kowalsld, MD, Insrimte of C~rdiology, Noninvasive Cardiology Department, Alpcjska 42, 04 628 W~rszawa, Poland. Copyright 9 I998 by the Americ~m Society of Echocardiography. 0894-7317/98 $500 + 0 27/1/93970 DISCUSSION A h i g h p r e v a l e n c e o f e m b o l i c events has b e e n n o t e d in individuals w i t h atrial septal aneurysm. 5 Aneurys. ms o f t h e v e n t r i c u l a r s e p t u m are i n f r e q u e n t . A m o n g c o m p l i c a t i o n s , an e m b o l i c p h e n o m e n a may occur. 1 In t h e past, it w a s s u g g e s t e d only at autopsy:4 Arora et al6 r e p o r t e d a case o f a 15-year-old girl w h o h a d a c u t e left h e m i p a r e s i s a s s o c i a t e d w i t h a t h r o m b u s f o r m e d inside t h e t r u e left v e n t r i c u l a r a n e u r y s m . W e h a v e n o t found, h o w e v e r , any r e p o r t c o n c e r n i n g a n e u r o l o g i c e v e n t that r e s u l t e d f r o m a t h r o m b u s formation within the aneurysm uf the interventricniar septum. We d e m o n s t r a t e d clots inside an a n e u r y s m a s s o c i a t e d w i t h c e r e b r a l infarct. V e n t r i c u l a r s e p t a l 1161 Journal of the American Society of Echocaxdiography December 1998 1162 Kowalski et al Figure 1 Lm'ge ventricular septal aneurysm (An) bulging into rigJat intlow tract visualized by moditied 4-chamber apical view. Two clots are seen inside sac. LA, Left atrium; /C4, right atrium; LV, left ventricle; RF, right ventricle. aneurysms should be looked for carefully with transthoracic echocardiography after an unexplained systemic embolism in children. REFERENCES 1. Bax0n MG, Wolf BS, Grishman A, Van Mierop LFI. Ameuxysm of the membranous septum. Am J Roentgenol 1964;91:1303 14. Figure 2 Parasternal short axis view of 2 dots inside interventricular aneurysm (An). LA, Left atrium; RA, right atrium; LV, left ventridr RV, right ventricIe. 2. Pombo E, pilapil VR, Lehan PH. Aneurysm of the membra nous ventricular septum. Am Heart I 1970;79:188-93. 3. GraffignaA, Minzioni G, RessiaL, Vigano M Sar~cai abla tion of ventricular tadaycardia secondary to congenital ven tricular septal aneurysm. Ann Thorac Surg 1994;$7:921-4. 4. Guccione F. Aneurismadissectante del setto interventricolare (pars membranocea). Arch di bin 1926;3:55-67. 5. BelkinRN, Hurwitz BJ, KissloJ. Atrial septal aneurysm:assoclarion with cerebrovascular and peripheral emboIic events. Stroke 1987;18:856-62. 6. Arora RP-, Issenberg I-II, Spindola-Franco t-I, Fayemi A, Steeg C. Congenital anettrysmof the left ventricle: its recognition and significance,lAMA 1988;259:3306-8. R e c e i v e t h e Journal's table o f c o n t e n t s e a c h m o n t h b y e-mail To receive the tables of contents by e-mail, send an e-mail message to majordomo@mosby.com L e a v e t h e s u b j e c t l i n e b l a n k , a n d t y p e t h e f o l l o w i n g as t h e b o d y o f y o u r m e s s a g e : Subscribe echo_toe Y o u c a n also s i g n u p t h r o u g h o u r W e b site a t http://www.mosby.com/echo You wii[ receive an e-mail message confirming that you have been added to the mailing list. N o t e t h a t T O C e - m a l l s will b e s e n t w h e n a n e w i s s u e is p o s t e d t o t h e W e b site.